Molecular Genetics Service Profile


AD-Multiple Epiphyseal Dysplasia

OMIM numbers - 132400, 600204, 600969, 607078, +120210


Introduction - Autosomal dominant Multiple Epiphyseal Dysplasia (AD-MED) is an osteochondrodysplasia affecting at least 1 in 10,000 individuals and is characterised by mild to moderate short stature and joint pain. AD-MED shows considerable genetic heterogeneity; mutations in the cartilage oligomeric matrix protein gene (COMP), the matrilin-3 gene (MATN3) and the genes encoding the α1, α2, and α3 chains of Type IX collagen (COL9A1, COL9A2, COL9A3) all cause AD-MED.

Referrals - We accept referrals from patients with a clinical/radiographic diagnosis or requiring a differential diagnosis of MED. We recommend that patients are first referred via the European Skeletal Dysplasia Network (www.esdn.org) case manager system where clinical details and X-rays are reviewed, at no cost, by an expert panel.

Technical - Bi-directional fluorescent sequencing of exons 8-19 of COMP, exon 2 of MATN3, exon 8 of COL9A1 and exon 3 of COL9A2 and COL9A3, including the splice donor and acceptor sites. If an unpublished missense change is identified we may request further family samples, when available, in order to assist in the interpretation.

Price and reporting times

TestPrice GBP(£)TRT *
COMP/MATN3/COL9 mutation scanning   483.00  40 
Single mutation test   138.00  10 
Prenatal diagnosis   276.00 

*Target reporting time in working days.

Test validation and quality assurance – information for users
Mutations are found in approximately 75% of referrals that have been diagnosed as MED by the ESDN case manager and screened for the genes listed above. Please note that the detection rate decreases if not referred via the ESDN.

The laboratory is a member of the UK Genetic Testing Network. www.ukgtn.org and has been accredited by Clinical Pathology UK Ltd since 1997 (centre 1932) www.cpa-uk.co.uk CPA standards are compliant with IS15189. The laboratory takes part in relevant External Quality Assessment Schemes (www.ukneqas.org.uk, www.emqn.org).

 

Further informaton

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Contact

National Genetics Reference
Laboratory (Manchester) and Regional Molectular Genetics Service

Department of Medical Genetics
St. Mary's Hospital
Hathersage Road
Manchester
M13 0JH
Tel: 0161 276 6122
Fax: 0161 276 6606

Sample Requirements:

COMP/MATN3/COL9 mutation scanning
  • Blood in EDTA
  • Adults 10ml
  • Children 5-10ml
  • Neonates 1ml min
  • Store at 4°C
  • Do not freeze
  • Send by 1st class post
Single mutation test
  • Blood in EDTA
  • Adults 10ml
  • Children 5-10ml
  • Neonates 1ml min
  • Store at 4°C
  • Do not freeze
  • Send by 1st class post
Prenatal diagnosis
  • 15µg of DNA extracted locally
  • CVS samples should be accompanied by a maternal sample
  • Send by 1st class post